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Episodic kinesigenic dyskinesia(EKD)

MedGen UID:
358268
Concept ID:
C1868682
Disease or Syndrome
Synonyms: EKD; Familial paroxysmal dystonia; Paroxysmal kinesigenic dyskinesia
SNOMED CT: Paroxysmal kinesigenic choreoathetosis (609221008); Paroxysmal kinesigenic dyskinesia (609221008)
Modes of inheritance:
Autosomal dominant inheritance
MedGen UID:
141047
Concept ID:
C0443147
Intellectual Product
Source: Orphanet
A mode of inheritance that is observed for traits related to a gene encoded on one of the autosomes (i.e., the human chromosomes 1-22) in which a trait manifests in heterozygotes. In the context of medical genetics, an autosomal dominant disorder is caused when a single copy of the mutant allele is present. Males and females are affected equally, and can both transmit the disorder with a risk of 50% for each child of inheriting the mutant allele.
Not genetically inherited
MedGen UID:
988794
Concept ID:
CN307044
Finding
Source: Orphanet
clinical entity without genetic inheritance.
 
Related gene: PRRT2
 
Monarch Initiative: MONDO:0044202
OMIM®: 128200
OMIM® Phenotypic series: PS128200
Orphanet: ORPHA98809

Definition

Paroxysmal kinesigenic choreoathetosis (PKC) is an autosomal dominant neurologic condition characterized by recurrent and brief attacks of involuntary movement triggered by sudden voluntary movement. These attacks usually have onset during childhood or early adulthood and can involve dystonic postures, chorea, or athetosis. Symptoms become less severe with age and show favorable response to anticonvulsant medications such as carbamazepine or phenytoin. It is the most common type of paroxysmal movement disorder. The condition is often misdiagnosed as an epileptic manifestation (summary by Chen et al., 2011). PKC shares some clinical features with benign familial infantile convulsions (BFIC2; 605751) and infantile convulsions and paroxysmal choreoathetosis (ICCA; 602066), which are allelic disorders. See also rolandic epilepsy with paroxysmal exercise-induced dystonia and writer's cramp (608105), which maps to chromosome 16p12-p11.2. Genetic Heterogeneity of Episodic Kinesigenic Dyskinesia See also EKD2 (611031), which maps to chromosome 16q13-q22.1, and EKD3 (620245), caused by mutation in the TMEM151A gene (620108) on chromosome 11q13. [from OMIM]

Professional guidelines

PubMed

Cao L, Huang X, Wang N, Wu Z, Zhang C, Gu W, Cong S, Ma J, Wei L, Deng Y, Fang Q, Niu Q, Wang J, Wang Z, Yin Y, Tian J, Tian S, Bi H, Jiang H, Liu X, Lü Y, Sun M, Wu J, Xu E, Chen T, Chen T, Chen X, Li W, Li S, Li Q, Song X, Tang Y, Yang P, Yang Y, Zhang M, Zhang X, Zhang Y, Zhang R, Ouyang Y, Yu J, Hu Q, Ke Q, Yao Y, Zhao Z, Zhao X, Zhao G, Liang F, Cheng N, Han J, Peng R, Chen S, Tang B
Transl Neurodegener 2021 Feb 16;10(1):7. doi: 10.1186/s40035-021-00231-8. PMID: 33588936Free PMC Article
De Gusmao CM, Silveira-Moriyama L
Expert Rev Neurother 2019 Sep;19(9):807-822. Epub 2019 Aug 8 doi: 10.1080/14737175.2019.1648211. PMID: 31353980
Bruno MK, Hallett M, Gwinn-Hardy K, Sorensen B, Considine E, Tucker S, Lynch DR, Mathews KD, Swoboda KJ, Harris J, Soong BW, Ashizawa T, Jankovic J, Renner D, Fu YH, Ptacek LJ
Neurology 2004 Dec 28;63(12):2280-7. doi: 10.1212/01.wnl.0000147298.05983.50. PMID: 15623687

Recent clinical studies

Diagnosis

Cuenca-Leon E, Cormand B, Thomson T, Macaya A
Neuropediatrics 2002 Dec;33(6):288-93. doi: 10.1055/s-2002-37079. PMID: 12571782

Clinical prediction guides

Liu D, Zhang Y, Wang Y, Chen C, Li X, Zhou J, Song Z, Xiao B, Rasco K, Zhang F, Wen S, Li G
Sci Rep 2016 May 13;6:25790. doi: 10.1038/srep25790. PMID: 27173777Free PMC Article
Cuenca-Leon E, Cormand B, Thomson T, Macaya A
Neuropediatrics 2002 Dec;33(6):288-93. doi: 10.1055/s-2002-37079. PMID: 12571782

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